Feasibility and Long-Term Compliance to Continuous Positive Airway Pressure Treatment in Adults With Down Syndrome, a Genetic Form of Alzheimer's Disease


Por: Gimenez, S, Farré A, Morente, F, Videla, L, Gutierrez, M, Clos, S, Fernandez, A, Blanco, M, Altuna, M, Pegueroles, J, Asensio, A, Benejam, B, Batista, M, Barroeta, I, Fortuna, A, Fortea, J, Mayos, M

Publicada: 30 mar 2022
Resumen:
BackgroundDown syndrome (DS) is a genetic form of Alzheimer's disease (AD) with a high prevalence of obstructive sleep apnea (OSA). These characteristics place the DS population as an optimal model to study the relationship between sleep and AD and to design clinical trials of preventive sleep therapies for AD. Regrettably, OSA treatment with continuous positive airway pressure (CPAP) is often neglected in adults with DS. In both clinical practice and research trials, it is usually presumed that these patients will not adapt to or tolerate the therapy. Study ObjectiveWe aimed to evaluate the feasibility and long-term CPAP compliance in this population and their capacity to be enrolled in CPAP research studies. MethodsWe prospectively compared the CPAP compliance of 17 OSA patients with DS and 19 age and sex matched OSA euploid patients. CPAP management and follow-up schedules were prescribed according to the habitual clinical practice. We compared group differences in tolerance, objective, and subjective hours of nightly CPAP usage at the 1st, 3rd, 6th, 12th, 24th, and 36th month visits. Good compliance was defined as at least 4 h use per night. We also investigated predictive factors of long-term CPAP compliance. ResultsThe percentage of DS subjects with good CPAP compliance (81.2 vs. 78.9%) and the objective CPAP use (5 vs. 6 h, p = 0.92) did not differ from the control group (CG). Subjective CPAP compliance was significantly higher in OSA patients with DS than in controls in all the follow-up visits (8 vs. 6.75 h, p = 0.001). The DS group had a significantly higher number of visits (9 vs. 5; p = 0.021) and mask changes (2.5 vs. 2; p = 0.05) than controls. Objective hours of CPAP use at the first follow-up visit predicted long-term CPAP compliance (p < 0.005). ConclusionCPAP treatment is feasible and has good long-term compliance in OSA patients with DS. It should be recommended to improve health and prevent comorbidities. The DS population is indeed suitable to participate in longitudinal preventive sleep clinical trials for AD.

Filiaciones:
Gimenez, S:
 Hosp Santa Creu & Sant Pau, Multidisciplinary Sleep Unit, Resp Dept, Biomed Res Inst St Pau, Barcelona, Spain

Farré A:
 Hosp Santa Creu & Sant Pau, Multidisciplinary Sleep Unit, Resp Dept, Biomed Res Inst St Pau, Barcelona, Spain

Morente, F:
 Hosp Santa Creu & Sant Pau, Multidisciplinary Sleep Unit, Resp Dept, Biomed Res Inst St Pau, Barcelona, Spain

Videla, L:
 Univ Autonoma Barcelona, Dept Neurol, St Pau Memory Unit, Hosp Santa Creu & St Pau,Biomed Res Inst St Pau, Barcelona, Spain

 Ctr Biomed Invest Network Neurodegenerat Dis CIBE, Madrid, Spain

 Fundacio Catalana Sindrome Down, Barcelona Down Med Ctr, Barcelona, Spain

Gutierrez, M:
 Hosp Santa Creu & Sant Pau, Multidisciplinary Sleep Unit, Resp Dept, Biomed Res Inst St Pau, Barcelona, Spain

Clos, S:
 Univ Autonoma Barcelona, Dept Neurol, St Pau Memory Unit, Hosp Santa Creu & St Pau,Biomed Res Inst St Pau, Barcelona, Spain

Fernandez, A:
 Hosp Santa Creu & Sant Pau, Multidisciplinary Sleep Unit, Resp Dept, Biomed Res Inst St Pau, Barcelona, Spain

Blanco, M:
 Hosp Santa Creu & Sant Pau, Multidisciplinary Sleep Unit, Resp Dept, Biomed Res Inst St Pau, Barcelona, Spain

Altuna, M:
 Univ Autonoma Barcelona, Dept Neurol, St Pau Memory Unit, Hosp Santa Creu & St Pau,Biomed Res Inst St Pau, Barcelona, Spain

 Ctr Biomed Invest Network Neurodegenerat Dis CIBE, Madrid, Spain

Pegueroles, J:
 Univ Autonoma Barcelona, Dept Neurol, St Pau Memory Unit, Hosp Santa Creu & St Pau,Biomed Res Inst St Pau, Barcelona, Spain

Asensio, A:
 Hosp Santa Creu & Sant Pau, Multidisciplinary Sleep Unit, Resp Dept, Biomed Res Inst St Pau, Barcelona, Spain

Benejam, B:
 Univ Autonoma Barcelona, Dept Neurol, St Pau Memory Unit, Hosp Santa Creu & St Pau,Biomed Res Inst St Pau, Barcelona, Spain

 Ctr Biomed Invest Network Neurodegenerat Dis CIBE, Madrid, Spain

 Fundacio Catalana Sindrome Down, Barcelona Down Med Ctr, Barcelona, Spain

Batista, M:
 Hosp Santa Creu & Sant Pau, Multidisciplinary Sleep Unit, Resp Dept, Biomed Res Inst St Pau, Barcelona, Spain

Barroeta, I:
 Univ Autonoma Barcelona, Dept Neurol, St Pau Memory Unit, Hosp Santa Creu & St Pau,Biomed Res Inst St Pau, Barcelona, Spain

 Ctr Biomed Invest Network Neurodegenerat Dis CIBE, Madrid, Spain

Fortuna, A:
 Hosp Santa Creu & Sant Pau, Multidisciplinary Sleep Unit, Resp Dept, Biomed Res Inst St Pau, Barcelona, Spain

Fortea, J:
 Univ Autonoma Barcelona, Dept Neurol, St Pau Memory Unit, Hosp Santa Creu & St Pau,Biomed Res Inst St Pau, Barcelona, Spain

 Ctr Biomed Invest Network Neurodegenerat Dis CIBE, Madrid, Spain

 Fundacio Catalana Sindrome Down, Barcelona Down Med Ctr, Barcelona, Spain

Mayos, M:
 Hosp Santa Creu & Sant Pau, Multidisciplinary Sleep Unit, Resp Dept, Biomed Res Inst St Pau, Barcelona, Spain

 Ctr Invest Biomed Red Enfermedades Resp CIBERNED, Madrid, Spain
ISSN: 16624548
Editorial
FRONTIERS MEDIA SA, AVENUE DU TRIBUNAL FEDERAL 34, LAUSANNE, CH-1015, SWITZERLAND, Suiza
Tipo de documento: Article
Volumen: 16 Número:
Páginas:
WOS Id: 000783950900001
ID de PubMed: 35431793
imagen gold, Green Published, All Open Access, Gold, Green

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