Characterizing circadian rest-activity rhythm patterns across Alzheimer's disease continuum in Down syndrome


Por: Giménez, S, Vaqué-Alcázar, L, Clos, S, Benejam, B, Carmona-Iragui, M, Maure-Blesa, L, Videla, L, Zhu, N, Altuna, M, Arranz, J, Barroeta, I, Rodríguez-Baz, I, Bejanin, A, Bueno, A, Fernandez, S, Soriano, LD, Pertierra, L, Alcolea, D, Miller, B, Grinberg, LT, Ruiz, J, Lisgaras, CP, Wu, H-, Lleó, A, Osorio, RS, Blessing, EM, Fortea, J

Publicada: 29 abr 2026
Resumen:
INTRODUCTION: Sleep and circadian rest-activity rhythm (RAR) disruption may bidirectionally relate to Alzheimer's disease (AD). Down syndrome (DS), the most common genetic cause of AD, presents sleep disorders, yet RAR patterns across the DS-associated AD continuum remain uncharacterized. METHODS: We analyzed 7-day wrist actigraphy in 140 adults with DS (108 asymptomatic; 32 AD dementia) and 41 unimpaired controls. General linear models, adjusted for age, sex, sleep efficiency, and obstructive sleep apnea (OSA) severity, tested group differences, with interaction terms included to evaluate group-specific associations. RESULTS: DS showed lower relative amplitude and higher nocturnal activity, already in asymptomatic individuals. Rhythm strength declined further with AD progression, while regularity and phase timing remained preserved until dementia. Findings were independent of sleep duration and OSA. DISCUSSION: Adults with DS showed early RAR disturbance that progressed across the AD continuum, paralleling sporadic AD. Circadian RAR features may be scalable biomarkers of AD progression.

Filiaciones:
Giménez, S:
 Hosp Santa Creu i St Pau, Biomed Res Inst St, Resp Dept, Multidisciplinary Sleep Unit,Pau IIB SANT PAU, Barcelona, Spain

 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

 Ctr Biomed Invest Network Neurodegenerat Dis CIBER, Madrid, Spain

 Univ Calif San Francisco, Global Brain Hlth Inst, San Francisco, CA USA

Vaqué-Alcázar, L:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

 Univ Barcelona, Inst Invest Biomed August Pi Sunyer IDIBAPS i, Fac Med & Hlth Sci, Inst Neurosci,Dept Med, Barcelona, Spain

Clos, S:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

Benejam, B:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

 Barcelona Med Ctr, Fundacio Catalana Sindrome, Barcelona, Spain

Carmona-Iragui, M:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

 Ctr Biomed Invest Network Neurodegenerat Dis CIBER, Madrid, Spain

 Barcelona Med Ctr, Fundacio Catalana Sindrome, Barcelona, Spain

Maure-Blesa, L:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

Videla, L:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

 Ctr Biomed Invest Network Neurodegenerat Dis CIBER, Madrid, Spain

 Barcelona Med Ctr, Fundacio Catalana Sindrome, Barcelona, Spain

Zhu, N:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

Altuna, M:
 CITA Alzheimer Fdn, Ctr Res & Memory Clin, San Sebastian, Spain

 Debabarrena Integrated Hlth Org, Osakidetza Basque Hlth Serv, Mendaro, Spain

 Araba Univ Hosp Txagorritxu, Hosp Araba, Bioaraba Hlth Res Inst, Dept Neurol, Vitoria, Spain

Arranz, J:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

Barroeta, I:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

 Ctr Biomed Invest Network Neurodegenerat Dis CIBER, Madrid, Spain

Rodríguez-Baz, I:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

 Ctr Biomed Invest Network Neurodegenerat Dis CIBER, Madrid, Spain

Bejanin, A:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

 Ctr Biomed Invest Network Neurodegenerat Dis CIBER, Madrid, Spain

Bueno, A:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

Fernandez, S:
 Barcelona Med Ctr, Fundacio Catalana Sindrome, Barcelona, Spain

Soriano, LD:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

 Ctr Biomed Invest Network Neurodegenerat Dis CIBER, Madrid, Spain

Pertierra, L:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

 Fleni Memory Clin, Neuropsychol & Neuropsychiat Unit, Cognit Neurol, Buenos Aires, Argentina

Alcolea, D:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

 Ctr Biomed Invest Network Neurodegenerat Dis CIBER, Madrid, Spain

Miller, B:
 Univ Calif San Francisco, Global Brain Hlth Inst, San Francisco, CA USA

 Univ Calif San Francisco, Edward & Pearl Fein Memory & Aging Ctr, San Francisco, CA USA

Grinberg, LT:
 Univ Calif San Francisco, Global Brain Hlth Inst, San Francisco, CA USA

 Mayo Clin, Dept Lab Med & Pathol & Neurosci, Jacksonville, FL USA

Ruiz, J:
 NYU Langone Hlth, Dept Psychiat, New York, NY USA

Lisgaras, CP:
 NYU Langone Hlth, Dept Psychiat, New York, NY USA

 New York State Off Mental Hlth, Nathan S Kline Inst Psychiat Res, Orangeburg, NY USA

Wu, H-:
 NYU, Courant Inst Math Sci, Dept Math, New York, NY USA

Lleó, A:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

 Ctr Biomed Invest Network Neurodegenerat Dis CIBER, Madrid, Spain

Osorio, RS:
 NYU Langone Hlth, Dept Psychiat, New York, NY USA

 New York State Off Mental Hlth, Nathan S Kline Inst Psychiat Res, Orangeburg, NY USA

Blessing, EM:
 NYU Langone Hlth, Dept Psychiat, New York, NY USA

 New York State Off Mental Hlth, Nathan S Kline Inst Psychiat Res, Orangeburg, NY USA

Fortea, J:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Biomed Res Inst St Pau IIB St Pau,IIB SANT PAU, Dept Neurol,St Pau Memory Unit, Barcelona, Spain

 Ctr Biomed Invest Network Neurodegenerat Dis CIBER, Madrid, Spain

 Barcelona Med Ctr, Fundacio Catalana Sindrome, Barcelona, Spain
ISSN: 15525260





ALZHEIMERS & DEMENTIA
Editorial
WILEY, 111 RIVER ST, HOBOKEN 07030-5774, NJ USA, Estados Unidos America
Tipo de documento: Article
Volumen: 22 Número: 5
Páginas:
WOS Id: 001754191200001
ID de PubMed: 42056071
imagen Green Submitted, hybrid

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