Toward European harmonization of national myasthenia gravis registries: modified Delphi procedure-based expert consensus on collectable data


Por: Slioui, A, Tammam, G, Vanoli, F, Della Marina, A, Vohanka, S, Gilhus, NE, Moroni, I, Leite, MI, Piehl, F, Antozzi, C, Pini, J, Stascheit, F, Attarian, S, Santos, E, Verschuuren, J, Canonge, L, Garcia, J, Perriard, C, Cortés-Vicente, E, Mantegazza, R, Meisel, A, Sacconi, S

Publicada: 11 mar 2025
Resumen:
BackgroundMyasthenia gravis (MG) is a rare autoimmune disorder. Several new treatment concepts have emerged in recent years, but access to these treatments varies due to differing national reimbursement regulations, leading to disparities across Europe. This highlights the need for high-quality data collection by stakeholders to establish MG registries. A European MG registry could help bridge the treatment access gap across different countries, offering critical data to support regulatory decisions, foster international collaborations, and enhance clinical and epidemiological research. Several national MG registries already exist or are in development. To avoid duplication and ensure harmonization in data collection, a modified Delphi procedure was implemented to identify essential data elements for inclusion in national registries.ResultsFollowing a literature review, consultations with patient associations and pharmaceutical companies, and input from multiple European MG experts, 100 data elements were identified. Of these, 62 reached consensus for inclusion and classification, while only 1 item was agreed for exclusion. 30 items failed to reach the >= 80% agreement threshold and were excluded. Among the 62 accepted items, 21 were classified as mandatory data elements, 32 optional, and 9 items pertained to the informed consent form.ConclusionsThrough a modified Delphi procedure, consensus was successfully achieved. This consensus-based approach represents a crucial step toward harmonizing MG registries across Europe. The resulting dataset will facilitate the sharing of knowledge and enhance European collaborations. Furthermore, the harmonized data may assist in regulatory or reimbursement decisions regarding novel therapies, as well as address treatment access disparities between European countries.

Filiaciones:
Slioui, A:
 Univ NICE, Nice Univ Hosp, Hop Pasteur 2, Pasteur Hosp 2,Reference Ctr Neuromuscular Disorde, 30 Voie Romaine, F-06000 Nice, France

Tammam, G:
 Univ NICE, Nice Univ Hosp, Hop Pasteur 2, Pasteur Hosp 2,Reference Ctr Neuromuscular Disorde, 30 Voie Romaine, F-06000 Nice, France

 Pavia Univ, Dept Brain & Behav Sci, IRCCS Fdn Mondino, Pavia, Italy

Vanoli, F:
 Fdn IRCCS Ist Neurol Carlo Besta, Neuroimmunol & Neuromuscular Dis Unit, Milan, Italy

 Sapienza Univ Rome, Dept Human Neurosci, Rome, Italy

Della Marina, A:
 Univ Hosp Essen, Dept Pediat Neurol, Ctr Neuromuscular Disorders, C TNBS, Essen, Germany

Vohanka, S:
 Masaryk Univ, Univ Hosp Brno, Dept Pediat Anesthesiol & Intens Care Med, Czechia, Brno, Czech Republic

Gilhus, NE:
 Univ Bergen, Dept Clin Med, Bergen, Norway

Moroni, I:
 Fdn IRCCS Ist Neurol Carlo Besta, Dept Pediat Neurosci, Milan, Italy

Leite, MI:
 Univ Oxford, John Radcliffe Hosp, Nuffield Dept Clin Neurosci, Level 3,West Wing,Headley Way, Oxford OX3 9DU, England

Piehl, F:
 Karolinska Univ Hosp, Karolinska Inst, Dept Clin Neurosci, Stockholm, Sweden

 Karolinska Univ Hosp, Dept Neurol, Stockholm, Sweden

Antozzi, C:
 Fdn IRCCS Ist Neurol Carlo Besta, Neuroimmunol & Neuromuscular Dis Unit, Milan, Italy

 Fdn IRCCS Ist Neurol Carlo Besta, Dept Neurol, Milan, Italy

Pini, J:
 Univ NICE, Nice Univ Hosp, Hop Pasteur 2, Pasteur Hosp 2,Reference Ctr Neuromuscular Disorde, 30 Voie Romaine, F-06000 Nice, France

Stascheit, F:
 Free Univ Berlin, Charitepl 1, D-10117 Berlin, Germany

 Univ Med Berlin, Humboldt Univ Berlin, Neurosci Clin Res Ctr, Dept Neurol Expt Neurol, Charitepl 1, D-10117 Berlin, Germany

Attarian, S:
 Aix Marseille Univ, Timone Univ Hosp, Reference Ctr Neuromuscular Disorders & ALS, Marseille, France

Santos, E:
 Univ Porto, CHU Santo Antonio, Unit Multidisciplinary Res Biomed UMIB, Unit Multidisciplinary Res Biomed,Inst Ciencias Bi, Porto, Portugal

Verschuuren, J:
 Leiden Univ, Med Ctr, Dept Neurol, Leiden, Netherlands

Canonge, L:
 Univ NICE, Nice Univ Hosp, Hop Pasteur 2, Pasteur Hosp 2,Reference Ctr Neuromuscular Disorde, 30 Voie Romaine, F-06000 Nice, France

 Univ Gustave Eiffel, ESIEE Paris, Paris, France

Garcia, J:
 Univ NICE, Nice Univ Hosp, Hop Pasteur 2, Pasteur Hosp 2,Reference Ctr Neuromuscular Disorde, 30 Voie Romaine, F-06000 Nice, France

Perriard, C:
 Nice Univ Hosp, Lenval Pediat Hosp, Reference Ctr Neuromuscular Disorders, Nice, France

Cortés-Vicente, E:
 Hosp Santa Creu & Sant Pau, Radiat Oncol, Barcelona, Spain

Mantegazza, R:
 Fdn IRCCS Ist Neurol Carlo Besta, Neuroimmunol & Neuromuscular Dis Unit, Milan, Italy

Meisel, A:
 Free Univ Berlin, Charitepl 1, D-10117 Berlin, Germany

 Univ Med Berlin, Humboldt Univ Berlin, Neurosci Clin Res Ctr, Dept Neurol Expt Neurol, Charitepl 1, D-10117 Berlin, Germany

Sacconi, S:
 Univ NICE, Nice Univ Hosp, Hop Pasteur 2, Pasteur Hosp 2,Reference Ctr Neuromuscular Disorde, 30 Voie Romaine, F-06000 Nice, France

 Univ Cote Azur, Hop Pasteur 2, IULS, CNRS,INSERM,SNPM Hop Pasteur 2, 30 Voie Romaine, F-06000 Nice, France
ISSN: 17501172





Orphanet Journal of Rare Diseases
Editorial
BMC, CAMPUS, 4 CRINAN ST, LONDON N1 9XW, ENGLAND, Reino Unido
Tipo de documento: Article
Volumen: 20 Número: 1
Páginas:
WOS Id: 001441791100003
ID de PubMed: 40069719
imagen Green Submitted, gold

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