Tumor analysis of MMR genes in Lynch-like syndrome: Challenges associated with results interpretation


Por: Rofes, P, Dueñas, N, del Valle, J, Navarro, M, Balmaña, J, Ramón y Cajal, T, Tuset, N, Castillo, C, González, S, Brunet, J, Capellá, G, Lázaro, C, Pineda, M

Publicada: 1 abr 2024
Resumen:
Background: Up to 70% of suspected Lynch syndrome patients harboring MMR deficient tumors lack identifiable germline pathogenic variants in MMR genes, being referred to as Lynch-like syndrome (LLS). Previous studies have reported biallelic somatic MMR inactivation in a variable range of LLS-associated tumors. Moreover, translating tumor testing results into patient management remains controversial. Our aim is to assess the challenges associated with the implementation of tumoral MMR gene testing in routine workflows. Methods: Here, we present the clinical characterization of 229 LLS patients. MMR gene testing was performed in 39 available tumors, and results were analyzed using two variant allele frequency (VAF) thresholds (>= 5% and >= 10%). Results and Discussion: More biallelic somatic events were identified at VAF >= 5% than >= 10% (35.9% vs. 25.6%), although the rate of nonconcordant results regarding immunohistochemical pattern increased (30.8% vs. 20.5%). Interpretation difficulties question the current utility of the identification of MMR somatic hits in the diagnostic algorithm of suspected LS cases.

Filiaciones:
Rofes, P:
 Catalan Inst Oncol, Inst Invest Biomed Bellvitge IDIBELL, Hereditary Canc Program, Mol Mech & Expt Therapy Oncol Program, Lhospitalet De Llobregat, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Dueñas, N:
 Catalan Inst Oncol, Inst Invest Biomed Bellvitge IDIBELL, Hereditary Canc Program, Mol Mech & Expt Therapy Oncol Program, Lhospitalet De Llobregat, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

del Valle, J:
 Catalan Inst Oncol, Inst Invest Biomed Bellvitge IDIBELL, Hereditary Canc Program, Mol Mech & Expt Therapy Oncol Program, Lhospitalet De Llobregat, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Navarro, M:
 Catalan Inst Oncol, Inst Invest Biomed Bellvitge IDIBELL, Hereditary Canc Program, Mol Mech & Expt Therapy Oncol Program, Lhospitalet De Llobregat, Spain

Balmaña, J:
 Vall dHebron Hosp, Vall dHebron Inst Oncol VHIO, Hereditary Canc Genet Grp, Barcelona, Spain

Ramón y Cajal, T:
 Hosp Santa Creu & Sant Pau, Med Oncol Dept, Barcelona, Spain

Tuset, N:
 Arnau de Vilanova Univ Hosp, Med Oncol Dept, Lleida, Spain

Castillo, C:
 Catalan Inst Oncol, Inst Invest Biomed Bellvitge IDIBELL, Hereditary Canc Program, Mol Mech & Expt Therapy Oncol Program, Lhospitalet De Llobregat, Spain

González, S:
 Catalan Inst Oncol, Inst Invest Biomed Bellvitge IDIBELL, Hereditary Canc Program, Mol Mech & Expt Therapy Oncol Program, Lhospitalet De Llobregat, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Brunet, J:
 Catalan Inst Oncol, Inst Invest Biomed Bellvitge IDIBELL, Hereditary Canc Program, Mol Mech & Expt Therapy Oncol Program, Lhospitalet De Llobregat, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

 Catalan Inst Oncol IDIBGI, Hereditary Canc Program, Girona, Spain

Capellá, G:
 Catalan Inst Oncol, Inst Invest Biomed Bellvitge IDIBELL, Hereditary Canc Program, Mol Mech & Expt Therapy Oncol Program, Lhospitalet De Llobregat, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Lázaro, C:
 Catalan Inst Oncol, Inst Invest Biomed Bellvitge IDIBELL, Hereditary Canc Program, Mol Mech & Expt Therapy Oncol Program, Lhospitalet De Llobregat, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

Pineda, M:
 Catalan Inst Oncol, Inst Invest Biomed Bellvitge IDIBELL, Hereditary Canc Program, Mol Mech & Expt Therapy Oncol Program, Lhospitalet De Llobregat, Spain

 Ctr Invest Biomed Red Canc CIBERONC, Madrid, Spain

 Catalan Inst Oncol, Hereditary Canc Program, IDIBELL, Av Gran Via 199-203, Lhospitalet De Llobregat 08908, Spain
ISSN: 20457634
Editorial
WILEY, 111 RIVER ST, HOBOKEN 07030-5774, NJ USA, Estados Unidos America
Tipo de documento: Article
Volumen: 13 Número: 7
Páginas:
WOS Id: 001194464900001
ID de PubMed: 38558366
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