Motor cortex transcriptome reveals microglial key events in amyotrophic lateral sclerosis


Por: Dols-Icardo, O, Montal, V, Sirisi, S, Lopez-Pernas, G, Cervera-Carles, L, Querol-Vilaseca, M, Munoz, L, Belbin, O, Alcolea, D, Molina-Porcel, L, Pegueroles, J, Turon-Sans, J, Blesa, R, Lleo, A, Fortea, J, Rojas-Garcia, R, Clarimon, J

Publicada: 1 sep 2020 Ahead of Print: 15 jul 2020
Resumen:
Objective To identify transcriptomic changes, neuropathologic correlates, and cellular subpopulations in the motor cortex of sporadic amyotrophic lateral sclerosis (ALS). Methods We performed massive RNA sequencing of the motor cortex of patients with ALS (n = 11) and healthy controls (HCs; n = 8) and analyzed gene expression alterations, differential isoform usage, and gene coexpression networks. Furthermore, we used cell type deconvolution algorithms with human single-nucleus RNA sequencing data as reference to identify perturbations in cell type composition associated with ALS. We performed immunohistochemical techniques to evaluate neuropathologic changes in this brain region. Results We report extensive RNA expression alterations at gene and isoform levels, characterized by the enrichment of neuroinflammatory and synaptic-related pathways. The assembly of gene coexpression modules confirmed the involvement of these 2 major transcriptomic changes, which also showed opposite directions related to the disease. Cell type deconvolution revealed an overrepresentation of microglial cells in ALS compared with HC. Notably, microgliosis was driven by a subcellular population presenting a gene expression signature overlapping with the recently described disease-associated microglia (DAM). Using immunohistochemistry, we further evidenced that this microglial subpopulation is overrepresented in ALS and that the density of pTDP43 aggregates negatively correlates with the proportion of microglial cells. Conclusions DAM has a central role in microglia-related neuroinflammatory changes in the motor cortex of patients with ALS, and these alterations are coupled with a reduced expression of postsynaptic transcripts.

Filiaciones:
Dols-Icardo, O:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Memory Unit, Dept Neurol, Barcelona, Spain

 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, St Pau Biomed Res Inst, Barcelona, Spain

 Network Ctr Biomed Res Neurodegenerat Dis CIBERNE, Madrid, Spain

Montal, V:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Memory Unit, Dept Neurol, Barcelona, Spain

 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, St Pau Biomed Res Inst, Barcelona, Spain

 Network Ctr Biomed Res Neurodegenerat Dis CIBERNE, Madrid, Spain

Sirisi, S:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Memory Unit, Dept Neurol, Barcelona, Spain

 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, St Pau Biomed Res Inst, Barcelona, Spain

 Network Ctr Biomed Res Neurodegenerat Dis CIBERNE, Madrid, Spain

Lopez-Pernas, G:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Memory Unit, Dept Neurol, Barcelona, Spain

 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, St Pau Biomed Res Inst, Barcelona, Spain

 Network Ctr Biomed Res Neurodegenerat Dis CIBERNE, Madrid, Spain

Cervera-Carles, L:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Memory Unit, Dept Neurol, Barcelona, Spain

 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, St Pau Biomed Res Inst, Barcelona, Spain

 Network Ctr Biomed Res Neurodegenerat Dis CIBERNE, Madrid, Spain

Querol-Vilaseca, M:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Memory Unit, Dept Neurol, Barcelona, Spain

 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, St Pau Biomed Res Inst, Barcelona, Spain

 Network Ctr Biomed Res Neurodegenerat Dis CIBERNE, Madrid, Spain

Munoz, L:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Memory Unit, Dept Neurol, Barcelona, Spain

 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, St Pau Biomed Res Inst, Barcelona, Spain

 Network Ctr Biomed Res Neurodegenerat Dis CIBERNE, Madrid, Spain

Belbin, O:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Memory Unit, Dept Neurol, Barcelona, Spain

 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, St Pau Biomed Res Inst, Barcelona, Spain

 Network Ctr Biomed Res Neurodegenerat Dis CIBERNE, Madrid, Spain

Alcolea, D:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Memory Unit, Dept Neurol, Barcelona, Spain

 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, St Pau Biomed Res Inst, Barcelona, Spain

 Network Ctr Biomed Res Neurodegenerat Dis CIBERNE, Madrid, Spain

Molina-Porcel, L:
 Hosp Clin Barcelona, Neurol Tissue Bank Biobanc, IDIBAPS, Barcelona, Spain

 Univ Barcelona, Hosp Clin, Dept Neurol, Alzheimers Dis & Other Cognit Disorders Unit,Inst, Barcelona, Spain

Pegueroles, J:
 Network Ctr Biomed Res Neurodegenerat Dis CIBERNE, Madrid, Spain

Turon-Sans, J:
 Network Ctr Biomed Res Rare Dis CIBERER, Madrid, Spain

 Univ Autonoma Barcelona, Dept Neurol, Neuromuscular Disorders Unit, Hosp Santa Creu & St Pau, Barcelona, Spain

Blesa, R:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Memory Unit, Dept Neurol, Barcelona, Spain

 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, St Pau Biomed Res Inst, Barcelona, Spain

 Network Ctr Biomed Res Neurodegenerat Dis CIBERNE, Madrid, Spain

Lleo, A:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Memory Unit, Dept Neurol, Barcelona, Spain

 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, St Pau Biomed Res Inst, Barcelona, Spain

 Network Ctr Biomed Res Neurodegenerat Dis CIBERNE, Madrid, Spain

Fortea, J:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Memory Unit, Dept Neurol, Barcelona, Spain

 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, St Pau Biomed Res Inst, Barcelona, Spain

 Network Ctr Biomed Res Neurodegenerat Dis CIBERNE, Madrid, Spain

Rojas-Garcia, R:
 Network Ctr Biomed Res Rare Dis CIBERER, Madrid, Spain

 Univ Autonoma Barcelona, Dept Neurol, Neuromuscular Disorders Unit, Hosp Santa Creu & St Pau, Barcelona, Spain

Clarimon, J:
 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, Memory Unit, Dept Neurol, Barcelona, Spain

 Univ Autonoma Barcelona, Hosp Santa Creu & St Pau, St Pau Biomed Res Inst, Barcelona, Spain

 Network Ctr Biomed Res Neurodegenerat Dis CIBERNE, Madrid, Spain
ISSN: 23327812
Editorial
LIPPINCOTT WILLIAMS & WILKINS, TWO COMMERCE SQ, 2001 MARKET ST, PHILADELPHIA, PA 19103 USA, Estados Unidos America
Tipo de documento: Article
Volumen: 7 Número: 5
Páginas:
WOS Id: 000571198600007
ID de PubMed: 32669313
imagen Gold, Green Published

MÉTRICAS